True pylorus duplication: a case report

Authors

  • Hala H. Mandora Clinical Science Department, Faculty of Medicine, Princess Nourah Bint Abdulrahman University, Riyadh, Saudi Arabia; Department of Surgery, King Abdullah bin Abdulaziz University Hospital, Riyadh, Saudi Arabia
  • Turki I. Al Nafisah Department of Surgery, King Abdullah bin Abdulaziz University Hospital, Riyadh, Saudi Arabia
  • Abdullah Y. Bamajboor Department of Surgery, King Abdullah bin Abdulaziz University Hospital, Riyadh, Saudi Arabia

DOI:

https://doi.org/10.18203/2349-2902.isj20241140

Keywords:

Pyloric duplication cyst, Case report, Pyloroplasty, Resection, Gastrointestinal duplication

Abstract

True pylorus duplication cysts are particularly rare, the literature describes only a small number of cases. They account for nearly 2.2% of all alimentary tract duplications. Most of the gastric duplications presents at an age younger than one year with one-third diagnosed in the neonatal period. However, they are not limited to that period. We report a case of a true pyloric duplication cyst in a 3-year-old girl who had been experiencing frequent vomiting with occasional abdominal pain for about 15 days prior to her presentation. The patient had an abdominal ultrasound that showed an epigastric cystic mass. CT of the abdomen demonstrated a 3.8×3.8 cm mass with a claw sign proximal to the first part duodenum. The diagnosis of pyloric duplication cyst was confirmed during the operation and with the histopathological examination following the resection. The patient is doing well with an appropriate weight gain at the follow-up appointments. The patient is doing well with an appropriate weight gain at the follow-up appointments. In summary, this is an an unusual case of gastric outlet obstruction that presented outside the usual age period caused by a pyloric duplication cyst. Imaging studies including US and CT are useful aids in the diagnoses of gastrointestinal duplication cysts.

References

Ladd WE. Duplications of the alimentary tract. South Med J. 1937;30(3):363-71.

Schalamon J, Schleef J, Hollworth ME. Experience with gastrointestinal duplications in childhood. Langenbeck’s Arch Surg. 2000;385(6):402-5.

Pruksapong C, Donovan RJ, Pinit A, Heldrich FJ. Gastric duplication. J Pediatr Surg. 1979;14(1):83-5.

Trainavicius K, Gurskas P, Povilavicius J. Duplication cyst of the pylorus: a case report. J Med Case Rep. 2013;7:175.

Ramsay GS. Enterogenous cyst of the stomach simulating hypertrophic pyloric stenosis. J Br Surg. 1957;44(188):632-3.

Mărginean CO, Mărginean C, Horváth E, Liliana G, Horea GG. Antenatally diagnosed congenital pyloric duplication associated with intraluminal pyloric cyst - rare entity case report and review of the literature. Rom J Morphol Embryol. 2014;55(3):983-8.

Saad DF, Gow KW, Shehata B. Pyloric duplication in a term newborn. J Pediatr Surg. 2005;40(7):1209-10.

Shah A, More B, Buick R. Pyloric duplication in a neonate: a rare entity. Pediatr Surg Int. 2005;21(3):220-22.

Hamada Y, Inoue K, Hioki K. Pyloroduodenal duplication cyst: case report. Pediatr Surg Int. 1997;12(2-3):194-5.

Puligandla PS, Nguyen LT, St-Vil D, Flageole H, Bensoussan AL, Nguyen VH, et al. Gastrointestinal duplications. J Pediatr Surg. 2003;38(5):740-44.

Guerin F, Guillaume Podevin, Petit T, Manuel L, Pascal L, Hubert L, et al. Outcome of alimentary tract duplications operated on by minimally invasive surgery: a retrospective multicentre study by the GECI. Surg Endosc. 2012;26(10):2848-55.

Arshad M, Jeelani SM, Siddiqui A, Rehan R. Duplication cyst of the pylorus: a rare cause of gastric outlet obstruction. BMJ Case Rep. 2018;2018:bcr2017223384.

Ahmed YB, Ghorbel S, Charieg A, Nouira F, Khemekhem R, Jlidi S, et al. Pyloric duplication: about two cases. J Pediatr Neonatal Care 2015; 2:00065.

Tang XB, Bai YZ, Wang WL. An intraluminal pyloric duplication cyst in an infant. J Ped Surg. 2008;43:2305-7.

Sharma D, Bharany RP, Mapshekhar RV. Duplication cyst of pyloric canal: a rare cause of pediatric gastric outlet obstruction: rare case report. Indian J Surg. 2013;75(1):322-5.

Orr M, Edward A. Neoplastic change in duplications of the alimentary tract. Br. J. Surg. 1975;62:269-74.

Patcharu R, Yadav J, Chand K, Parikh B. Intraluminal pyloric duplication cyst- a rare cause of non-bilious vomiting in a neonate: A case report. J Neonatal Surg. 2021;10:44.

Downloads

Published

2024-04-29

Issue

Section

Case Reports